The Emergence of Effortful Control in Young Boys With Fragile X Syndrome-Reference-Cited by-同舟云学术

The Emergence of Effortful Control in Young Boys With Fragile X Syndrome

Published:2018-03-01 Issue:2 Volume:123 Page:89-102
ISSN:1944-7515
Container-title:American Journal on Intellectual and Developmental Disabilities
language:en
Short-container-title:

Author:

Robinson Marissa¹,Klusek Jessica²,Poe Michele D.³,Hatton Deborah D.⁴,Roberts Jane E.⁵

Affiliation:

1. Marissa Robinson, University of South Carolina, Department of Psychology;

2. Jessica Klusek, University of South Carolina, Department of Communication Sciences and Disorders;

3. Michele D. Poe, University of Pittsburgh, Program for the Study of Neurodevelopment in Rare Disorders, Pittsburgh,

4. Deborah D. Hatton, Vanderbilt University, Department of Special Education; and

5. Jane E. Roberts, University of South Carolina, Department of Psychology.

Abstract

Abstract Effortful control, or the ability to suppress a dominant response to perform a subdominant response, is an early-emerging temperament trait that is linked with positive social-emotional development. Fragile X syndrome (FXS) is a single-gene disorder characterized by hallmark regulatory impairments, suggesting diminished effortful control. This study compared the development of effortful control in preschool boys with FXS (n = 97) and typical development (n = 32). Unlike their typical peers, the boys with FXS did not exhibit growth in effortful control over time, which could not be accounted for by adaptive impairments, FMR1 molecular measures, or autism symptoms. These results contribute to our understanding of the childhood phenotype of FXS that may be linked to the poor social-emotional outcomes seen in this group.

Publisher

American Association on Intellectual and Developmental Disabilities (AAIDD)

Subject

Psychiatry and Mental health,Neurology (clinical),Arts and Humanities (miscellaneous),Developmental and Educational Psychology,Neuropsychology and Physiological Psychology,General Medicine,Pediatrics, Perinatology and Child Health

Link

http://meridian.allenpress.com/ajidd/article-pdf/123/2/89/2029624/1944-7558-123_2_89.pdf

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3. Early Intervention;Handbook of Intellectual Disabilities;2019