Ankyloglossia in Children, a Cause of Obstructive Sleep Apnoea: Case Report of Paediatric Ankyloglossia and Sleep Apnoea: DISE Resolves the Mystery-Reference-Cited by-同舟云学术

Ankyloglossia in Children, a Cause of Obstructive Sleep Apnoea: Case Report of Paediatric Ankyloglossia and Sleep Apnoea: DISE Resolves the Mystery

Published:2024-02-08 Issue:2 Volume:11 Page:218
ISSN:2227-9067
Container-title:Children
language:en
Short-container-title:Children

Author:

Valderrama-Penagos Johanna Ximena¹,Rodríguez Alcalá Laura¹^ORCID,Plaza Guillermo²^ORCID,Baptista Peter³^ORCID,Garcia Iriarte Maria Teresa⁴^ORCID,Correa Eduardo J.⁵^ORCID,O’Connor-Reina Carlos¹^ORCID

Affiliation:

1. Department of Otorhinolaryngology, Hospital Quiron Salud Marbella, Av. Severo Ochoa 22, 29603 Marbella, Spain

2. Department of Otorhinolaryngology, Hospital Fuenlabrada, Universidad Rey Juan Carlos I, 28032 Madrid, Spain

3. Department of Otorhinolaryngology, Clinica Universitaria de Navarra, 31008 Pamplona, Spain

4. Department of Otorhinolaryngology, Hospital Universitario Virgen de Valme, 41014 Seville, Spain

5. Department of Otorhinolaryngology, Hospital La Linea, 11300 La Linea de la Concepción, Spain

Abstract

Tongue mobility is an obstructive sleep apnoea (OSA) marker and myofunctional therapy (MFT) target. For this reason, all paediatric patients with sleep-disordered breathing should require a combined functional assessment from an ear, nose, and throat (ENT) specialist and a phonoaudiologist to confirm or rule out the presence of ankyloglossia. To our knowledge, this is the first case of a 13-year-old girl diagnosed with severe OSA and a significant decrease of 94% in her apnoea index (AI), requiring frenotomy with an immediate postoperative change in the tongue position. A drug-induced sleep endoscopy (DISE) was performed before and immediately postfrenotomy, and the anatomical changes provoked by this surgery during sleep were confirmed for the first time.

Publisher

MDPI AG

Link

https://www.mdpi.com/2227-9067/11/2/218/pdf

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