Wilson's Disease Masquerading as Acute Encephalitis: A Case Report

Author:

Kalwar Asifa1,Rid Quratulain2,Ahsan Sadia2,Ochani Sidhant3ORCID

Affiliation:

1. Dow University of Health Sciences

2. Shaheed Montarma Benazir Bhutto Medical University Ghulam Muhammad Mahar Medical College

3. Khairpur Medical College

Abstract

Abstract

Introduction: Wilson's disease (WD) is a rare autosomal recessive disorder characterized by copper accumulation in the liver, brain, and cornea, resulting from mutations in the ATP7B gene. Case Presentation: This case report presents a unique manifestation of WD, as a 14-year-old female from rural Pakistan presented with acute encephalitis and the ‘Face of the Giant Panda Sign’. Encephalitis is an uncommon initial presentation of WD, and this case highlights the diagnostic challenges, especially in resource-limited settings. The patient exhibited sudden-onset fever, generalized tonic-clonic seizures, and altered mental status. Initially misattributed to possession by the parents, the patient underwent empirical treatment for encephalitis in the hospital without improvement. Further evaluation revealed abnormal liver function, positive HepBsAg, and characteristic brain MRI findings indicative of WD. Confirmation was made through low ceruloplasmin, Kayser-Fleischer rings, and modified Leipzig criteria. Treatment with penicillamine and vitamin B6 resulted in clinical improvement. Conclusion This case emphasizes the importance of considering WD in cases of encephalitis, even in the absence of typical hepatic symptoms. The delay in diagnosis and initial misinterpretation underscore the need for increased awareness and education, particularly in regions with limited healthcare resources. Early recognition and intervention can prevent the progression of WD, improving patient outcomes. The report also underscores the significance of familial screening and long-term follow-up to manage the chronic nature of the disease. Further studies and reporting of atypical presentations contribute to the understanding and management of this rare and clinically heterogeneous disorder.

Publisher

Springer Science and Business Media LLC

Reference25 articles.

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