Chronic Recurrent Multifocal Osteomyelitis in Pediatric patients: A Case Series Study from China and Literature review

Author:

Hu Minhua1,Zeng Wenxing1,Zhang Jingtao1,Yan Hongsong1,Huang Feng1,Xiong Hao2,Fang Bin2,Li Yue2

Affiliation:

1. Guangzhou University of Chinese Medicine

2. The First Affiliated Hospital of Guangzhou University of Chinese Medicine

Abstract

Abstract

Background Chronic recurrent multifocal osteomyelitis (CRMO) is a rare auto-inflammatory disorder that often pose diagnostic challenges due to its atypical symptomatology. This retrospective study aimed to investigate the clinical features, laboratory tests, imaging features, and treatment strategies of CRMO in pediatric patients. Methods In the study, seven pediatric patients with CRMO treated at the Department of Pediatric Orthopedics, First Affiliated Hospital of Guangzhou University of Chinese Medicine, between January 2018 and February 2022, were retrospectively analyzed. The objective was to enhance understanding of CRMO by exploring clinical data in-depth. Results The study group comprised five males and two females, aged 3 to 13 years. They experienced symptoms for a median duration of 6 months before hospitalization, presenting with recurrent pain and various accompanying signs, including hypothermia (one case, 14.28%), swelling (three cases, 42.85%), localized skin warmth (three cases, 42.85%), and plantar pustules (one case, 14.28%). The femur (five cases,71.42%) and tibia (five cases, 71.42%) were frequently affected. Radiographic and CT scans showed osteosclerosis and osteolytic lesions, while MRI detected bone marrow edema. Histological examination of bone biopsies from four patients revealed fibrous tissue hyperplasia, lymphocytic, and neutrophilic infiltration, despite negative bacterial cultures. Laboratory tests generally showed normal or slightly elevated values. Symptomatic improvement was observed in six patients (85.72%) with nonsteroidal anti-inflammatory drugs (NSAIDs), while one patient (14.28%) resistant to NSAIDs responded well to tumor necrosis factor (TNF) inhibitors. Conclusions In summary, CRMO's clinical presentation lacks specificity, with unexplained bone pain being the most common symptom. Precise diagnosis and timely intervention depend on thorough MRI evaluation for lesion detection, enhancing CRMO diagnosis. This study offers valuable insights into CRMO's clinical manifestations, laboratory findings, imaging features, and treatment strategies in pediatric patients.

Publisher

Springer Science and Business Media LLC

Reference52 articles.

1. Nonbacterial osteitis in children: data of a German Incidence Surveillance Study;Jansson AF;Acta Paediatr,2011

2. Subacute and chronic symmetrical osteomyelitis;Giedion A;Ann Radiol (Paris),1972

3. Radiological aspect of chronic recurrent multifocal osteomyelitis;Probst FP;Ann Radiol (Paris),1978

4. New Insights into Adult and Paediatric Chronic Non-bacterial Osteomyelitis CNO;Hedrich CM;Curr Rheumatol Rep,2020

5. Clinical outcome in children with chronic recurrent multifocal Osteomyelitis;Catalano-Pons C;Rheumatology (Oxford),2008

同舟云学术

1.学者识别学者识别

2.学术分析学术分析

3.人才评估人才评估

"同舟云学术"是以全球学者为主线,采集、加工和组织学术论文而形成的新型学术文献查询和分析系统,可以对全球学者进行文献检索和人才价值评估。用户可以通过关注某些学科领域的顶尖人物而持续追踪该领域的学科进展和研究前沿。经过近期的数据扩容,当前同舟云学术共收录了国内外主流学术期刊6万余种,收集的期刊论文及会议论文总量共计约1.5亿篇,并以每天添加12000余篇中外论文的速度递增。我们也可以为用户提供个性化、定制化的学者数据。欢迎来电咨询!咨询电话:010-8811{复制后删除}0370

www.globalauthorid.com

TOP

Copyright © 2019-2024 北京同舟云网络信息技术有限公司
京公网安备11010802033243号  京ICP备18003416号-3