Integrative Genetics and Multiomics Analysis Unveil Mechanisms and Therapeutic Targets in Vitiligo: Insights from GWAS-meta, Microarray, Single-cell Transcriptomics, and ChIP-seq Data, Highlighting JAK/STAT Pathway Regulation of CTSS in Vitiligo

Author:

Dong Zi-yue1ORCID,He Ming-jie1,Yu Yong-kai2,wang Kun1,Wang Fang1,Ran De-long1,Fu De-shuang1,He Qing1,Yang Run-ping3,Zhang Jiang-an1

Affiliation:

1. The First Affiliated Hospital of Zhengzhou University

2. Jiangsu Province Hospital and Nanjing Medical University First Affiliated Hospital Liver Transplantation Center: The First Affiliated Hospital With Nanjing Medical University Department of General Surgery

3. Sixth Medical Center of PLA General Hospital

Abstract

Abstract

Background: Vitiligo is a complex autoimmune disease characterized by the loss of melanocytes, leading to skin depigmentation. Despite advances in understanding its genetic and molecular basis, the precise mechanisms driving vitiligo remain elusive. Integrating multiple layers of omics data can provide a comprehensive view of disease pathogenesis and identify potential therapeutic targets. Methods: We first performed a genome-wide association study (GWAS) meta-analysis and druggability assessment using the latest data from FinnGen, the GWAS Catalog, and the UK Biobank. We subsequently investigated pathogenic and protective genes associated with vitiligo via summary-based Mendelian randomization (SMR) analysis across multiple eQTL and pQTL databases to construct a transcription factor regulatory network. Finally, we validated the genetically associated and causal genes identified in the previous analyses via microarray and single-cell RNA sequencing data. Results: The GWAS-meta analysis identified five genes with potential druggability: ERBB3, RHOH, CDK10, MC1R, and NDUFAF3. Drug target exploration and molecular docking were performed for these genes. SMR analysis revealed that five genes—CTSS, CTSH, STX8, KIR2DL3, and GRHPR—are causally associated with vitiligo at both the pQTL and eQTL levels. By integrating microarray and single-cell transcriptomic data, we detected differential expression of CTSS and its transcription factor STAT1/3 in both the blood and lesional skin of vitiligo patients. Conclusions: Our integrative multiomics approach provides new insights into the genetic and molecular mechanisms underlying vitiligo. The JAK/STAT pathway may contribute to vitiligo pathogenesis by regulating CTSS, which is involved in melanocyte antigen processing and presentation. Future research should focus on validating these findings and exploring the therapeutic potential of CTSS and genetically associated genes.

Publisher

Springer Science and Business Media LLC

同舟云学术

1.学者识别学者识别

2.学术分析学术分析

3.人才评估人才评估

"同舟云学术"是以全球学者为主线,采集、加工和组织学术论文而形成的新型学术文献查询和分析系统,可以对全球学者进行文献检索和人才价值评估。用户可以通过关注某些学科领域的顶尖人物而持续追踪该领域的学科进展和研究前沿。经过近期的数据扩容,当前同舟云学术共收录了国内外主流学术期刊6万余种,收集的期刊论文及会议论文总量共计约1.5亿篇,并以每天添加12000余篇中外论文的速度递增。我们也可以为用户提供个性化、定制化的学者数据。欢迎来电咨询!咨询电话:010-8811{复制后删除}0370

www.globalauthorid.com

TOP

Copyright © 2019-2024 北京同舟云网络信息技术有限公司
京公网安备11010802033243号  京ICP备18003416号-3